AbstractThe case reported here refers to the skeletal remains of a mature adult male found in a collective grave known as ‘Giant's tomb’ located near Donori (Sardinia) and dating to the end of the Bronze Age. The skeleton showed bilateral shortening of the forearm associated to radial bowing, marked deformations at the radio‐ulnar distal joints and subsequent posterior dislocation of both ulnae. The whole alterations fit well with a diagnosis of Madelung's deformity, a rare form of mesomelic dysplasia. At present, this case is the most ancient evidence of Madelung's deformity. Copyright © 2002 John Wiley & Sons, Ltd.