The West Nile virus (WNV) is a widely distributed emerging mosquito-borne arbovirus. Although the majority of WNV infections are asymptomatic (80%), some infected individuals (20%) present with non- specific febrile disease (WNV fever) and less than 1% develop neuroinvasive diseases (meningitis, encephalitis, and myelitis). Several atypical or rare presentations of WNV infection such as cerebellitis, myocarditis, hepatitis, pancreatitis, and rhabdomyolysis have been described in case reports or small case series1. Although rare, ocular manifestations, including monofocal or multifocal WNV chorioretinitis are the most commonly reported clinical manifestations of WNV infection after fever and neuroinvasive disease.