Fusarium is a filamentous fungus widely distributed in plants and in the soil. Most species are more common at tropical and subtropical areas. Besides being a common contaminant and a well-known plant pathogen, Fusarium sp may cause various infections in humans. However, it has not yet been reported as being the pathogen of urinary tract infection. A 67-year-old woman had extracorporeal shock wave lithotripsy and percutaneous nephrolithotomy for renal stones 7 and 6 years ago, respectively. She had had fever, chillness, urinary urgency and frequency for 6 days. Routine testing of urine showed numerous leucocytes. She was admitted under the impression of urinary tract infection. On admission, many spindle-shaped structures were found in the urine smears. This shows that Fusarium was identified. Fusarium may be the pathogen of the urinary tract infection, particularly when urolithiasis is present.