Intramuscular myxomas of the head and neck are rare entities. Primarily found in the myocardium, these lesions also affect the bones and soft tissues. We present a case of an intramuscular myxoma of the temporalis muscle. After reviewing the literature, this case constitutes, to our knowledge, the second reported occurrence of a myxoma in this specific location. The patient was treated for this condition with an excisional biopsy after fine needle aspiration revealed a benign process. No recurrence was seen 18 months after the excision.